Effect of spinal cord stimulation in Type I complex regional pain syndrome with 2 rare severe cutaneous manifestations

Case report

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  • 1 Department of Neurosurgery, Maastricht University Hospital, Maastricht; and
  • 2 Department of Neurosurgery, Alkmaar Medical Centre, Alkmaar, The Netherlands
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The authors present the case of a 49-year-old female patient with complex regional pain syndrome–Type I (CRPSI) who was suffering from nonhealing wounds and giant bullae, which dramatically improved after spinal cord stimulation (SCS). The scientific literature concerning severe cutaneous manifestations of CRPS-I and their treatment is reviewed. Nonhealing wounds and bullae are rare manifestations of CRPS-I that are extremely difficult to treat. Immediate improvement of both wounds and bullae after SCS, such as in this case, has not been reported previously in literature. Considering the rapidly progressive nature of these severe skin manifestations, immediate treatment, possibly with SCS, is mandatory.

Abbreviations used in this paper: CRPS = complex regional pain syndrome; SCS = spinal cord stimulation.

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Contributor Notes

Address correspondence to: Kim Rijkers, M.D., Department of Neurosurgery, Maastricht University Hospital, P. Debyelaan 25, PO Box 5800, 6202 AZ Maastricht, The Netherlands. email: kimrijkers@gmail.com.
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